Nemaline myopathy type 2 (NEM2): two novel mutations in the nebulin (NEB) gene.
نویسندگان
چکیده
Nemaline myopathy is a type of the heterogeneous group of congenital myopathies. Generalized hypotonia, weakness, and delayed motor development are the main clinical features of the typical congenital form. Histopathology shows characteristic nemaline rods in the muscle biopsy. Mutations in at least 7 genes, including nebulin gene (NEB), proved to be responsible for this muscle disease. We present a boy with nemaline myopathy type 2 (NEM2) caused by compound heterozygosity for 2 novel mutations, a deletion and a duplication in the NEB gene. The deletion was inherited from the father and the duplication from the mother. Testing all family members supports genetic counseling.
منابع مشابه
neb: a zebrafish model of nemaline myopathy due to nebulin mutation
Nemaline myopathy is one of the most common and severe non-dystrophic muscle diseases of childhood. Patients typically present in infancy with hypotonia, weakness, delayed motor development, and bulbar and respiratory difficulties. Mutations in six different genes are associated with nemaline myopathy, with nebulin mutations being the most common. No treatments or disease-modifying therapies ha...
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متن کاملPii: S0960-8966(00)00177-2
Nemaline myopathy is a structural congenital myopathy which may show both autosomal dominant and autosomal recessive inheritance patterns. Mutations in three different genes have been identi®ed as the cause of nemaline myopathy: the gene for slow a-tropomyosin 3 (TPM3) at 1q22±23, the nebulin gene (NEB) at 2q21.1±q22, and the actin gene (ACTA1) at 1q42. The typical autosomal recessive form appe...
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Nemaline myopathy (NM) is the most common non-dystrophic congenital myopathy. Clinically the most important feature of NM is muscle weakness; however, the mechanisms underlying this weakness are poorly understood. Here, we studied the muscular phenotype of NM patients with a well-defined nebulin mutation (NM-NEB), using a multidisciplinary approach to study thin filament length regulation and m...
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عنوان ژورنال:
- Journal of child neurology
دوره 30 5 شماره
صفحات -
تاریخ انتشار 2015